Odontogenic keratocyst (OKC) of the maxillary sinus is very rare and occupies less than 1% of the total number of cases reported in the previous literatures with a highly susceptible to secondary infection and recurrence. This case report presents a female patient with swelling and persistent discharge of pus from the left upper posterior dental region. Patient underwent the necessary basic and advanced microbiological and radiological investigations showed an unusual instance of OKC of maxillary sinus with Klebsiella infection. The patient underwent surgical intervention following cyst enucleation with chemical cauterization under General anaesthesia resulting in successful management and resolution of symptoms. The case report provides additional insights into the infected odontogenic keratocyst of maxillary sinus drawing upon the existing body of literature on previously reported cases.
Keywords: Dontogenic keratocyst, Maxillary sinus, Cyst enucleation, Carnoy’s, Klebsiella infection.
